Jan 2026· Case Reports in Genetics· Vol 2026· 0 citations· 33 references
Medicine
TL;DR
A patient with an intermediate CMT (CMT‐Int) type carrying a novel pathogenic variant in the MPZ gene combined with type 2 diabetes developed type 2 diabetes following pancreatic cyst surgery in September 2022, and Electrophysiological findings suggested widespread peripheral nerve damage affecting both sensory and motor fibers.
Abstract
Charcot–Marie–Tooth (CMT) disease is the collective term for the most common inherited peripheral neuropathies, affecting both motor and sensory nerves. A typical CMT patient presents with slowly progressive distal muscle weakness and atrophy that primarily involves the small foot muscles, peroneal muscles, and, often later, the muscles of the hands and forearms. Foot deformities, most commonly pes cavus and claw toes, are common and can lead to gait impairments. In this paper, we report a patient with an intermediate CMT (CMT‐Int) type carrying a novel pathogenic variant in the MPZ gene combined with type 2 diabetes. The patient’s initial symptoms included a gradual onset of muscle wasting, weakness, and sensory impairment in the lower limbs. Electrophysiological findings suggested widespread peripheral nerve damage affecting both sensory and motor fibers, with a predominant demyelinating pattern accompanied by axonal damage. Genetic testing identified a previously unreported heterozygous mutation in the MPZ gene, specifically c.548G > A, p.Trp183∗. This alteration results in the replacement of the 183rd amino acid (tryptophan) by a stop codon. This premature stop codon is predicted to escape nonsense‐mediated mRNA decay, resulting in a C‐terminally truncated protein that may exert a dominant‐negative effect. Although a different variant affecting the same codon (c.549G > A, p.Trp183∗, VCV000917145.1) has been documented, this particular pathogenic mutation has not been previously recorded. After being diagnosed with CMT, the patient developed type 2 diabetes following pancreatic cyst surgery in September 2022. The presence of both conditions exposed her peripheral nerves to congenital structural abnormalities combined with the metabolic consequences of chronic hyperglycemia and local ischemia, thereby exacerbating nerve injury.
Hereditary sensorimotor neuropathies are characterized by high genetic heterogeneity, which complicates their diagnosis. Autosomal recessive axonal neuropathy with neuromyotonia (ARAN-NM), associated with mutations in the HINT1 gene, is a rare but clinically recognizable disease. Description of clinical cases is import...
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Charcot–Marie–Tooth (CMT) disease is an inherited motor and sensory neuropathy that typically presents with cavovarus foot deformity. Pes planovalgus is uncommon in CMT and, while noted incidentally in multicenter cohort studies of CMT4B subtypes, has not been described as the predominant orthopedic manifestation in a...
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Charcot-Marie-Tooth (CMT) is a group of inherited neuromuscular disorders with diverse clinical features such as muscle weakness and atrophy of the distal regions, foot deformities, sensory loss and decreased or absent reflexes. With the diverse inheritance patterns including dominant, recessive, and X-linked, it exhib...
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This research contributed to the genetic assessment and guidance for two families affected by Charcot–Marie–Tooth disease, reinforcing the notion that MORC2 is a potential causative gene for CMT2Z.
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