A proof-of-concept study supports the promise of CD4-NBs as a minimally invasive, CD4⁺ cell-targeted gene editing strategy for HIV therapy and reduces viremia in ART-pretreated humanized mice.
Abstract
Current antiretroviral therapies suppress HIV replication but fail to eliminate integrated proviral DNA in long-lived CD4⁺ cells, precluding a cure. CRISPR-Cas9 offers potential for HIV eradication but efficient and cell-specific delivery into HIV target cells remains a major hurdle. We developed CD4-directed Nanoblades (CD4-NBs), murine leukemia virus-like particles pseudotyped with anti-CD4 nanobodies and a fusogenic glycoprotein VSV Gmut, to selectively deliver Cas9-gRNA ribonucleoproteins into CD4⁺ cells. CD4-NBs selectively delivered cargo to CD4⁺ cells in vitro and in vivo, achieving efficient gene disruption in primary CD4+ cells. Dual-guide CD4-NBs targeting conserved HIV tat/rev/env regions disrupted proviral DNA, suppressing HIV infection in CD4+ cells. In HIV-infected, ART-pretreated humanized mice, CD4-NBs significantly reduced plasma viremia. While full tissue reservoir clearance was not achieved, repeated dosing did reduce viral RNA and proviral DNA in bone marrow and lungs, respectively. As such, this proof-of-concept study supports the promise of CD4-NBs as a minimally invasive, CD4⁺ cell-targeted gene editing strategy for HIV therapy. Virus-like particles engineered with anti-CD4 nanobodies (i.e., CD4-directed nanoblades) present a promising HIV cure strategy as they achieve CD4+ cell-specific CRISPR-Cas9 delivery, efficient gene editing, HIV proviral DNA disruption and reduced viremia in ART-pretreated humanized mice. CD4-NBs were engineered by pseudotyping murine leukemia virus-like particles with anti-CD4 nanobodies and a fusogenic glycoprotein to enable targeted Cas9-gRNA ribonucleoprotein delivery. Selective cargo delivery was achieved in vitro and in vivo, with efficient gene disruption observed specifically in (primary) CD4⁺ cells. HIV proviral DNA was disrupted using dual-guide CD4-NBs targeting conserved HIV tat/rev/env regions, resulting in suppressed HIV infection in CD4⁺ cells. In HIV-infected, ART-pretreated humanized mice, viremia was significantly reduced following CD4-NB administration. Repeated CD4-NB dosing was associated with reductions in viral RNA and proviral DNA in bone marrow and lungs, respectively, though full tissue reservoir clearance was not achieved. CD4-NBs were engineered by pseudotyping murine leukemia virus-like particles with anti-CD4 nanobodies and a fusogenic glycoprotein to enable targeted Cas9-gRNA ribonucleoprotein delivery. Selective cargo delivery was achieved in vitro and in vivo, with efficient gene disruption observed specifically in (primary) CD4⁺ cells. HIV proviral DNA was disrupted using dual-guide CD4-NBs targeting conserved HIV tat/rev/env regions, resulting in suppressed HIV infection in CD4⁺ cells. In HIV-infected, ART-pretreated humanized mice, viremia was significantly reduced following CD4-NB administration. Repeated CD4-NB dosing was associated with reductions in viral RNA and proviral DNA in bone marrow and lungs, respectively, though full tissue reservoir clearance was not achieved. Virus-like particles engineered with anti-CD4 nanobodies (i.e., CD4-directed nanoblades) present a promising HIV cure strategy as they achieve CD4+ cell-specific CRISPR-Cas9 delivery, efficient gene editing, HIV proviral DNA disruption and reduced viremia in ART-pretreated humanized mice.
Total elimination of replication-competent human immunodeficiency virus type 1 (HIV-1) remains a major clinical challenge, in part due to random integration of the proviral DNA into host cell chromosomes, which enables lifelong persistence and production of progeny. Although antiretroviral therapies (ARTs) suppress viral replication, they cannot eliminate integrated proviral DNA, which remains a fundamental obstacle to achieving a cure. To overcome this problem, we developed a combinatorial clustered regularly interspaced short palindromic repeats-Cas9 gene editing strategy to disrupt viral replication and inactivate host factors essential for HIV-1 entry and spread. This approach targets C-C chemokine receptor type 5 (CCR5), a chemokine receptor central to HIV-1 host cell entry, and mannosyl-oligosaccharide glucosidase (MOGS), a key enzyme in glycoprotein processing that modifies the HIV-1 envelope glycoprotein gp120, facilitating receptor engagement, viral entry, and morphogenesis of infectious virion. We demonstrate that our strategy, which includes editing of the integrated proviral DNA, in concert with two cellular genes whose products facilitate viral entry, results in robust suppression of viral replication in vitro and in ex vivo-infected cells. Using transmission electron microscopy, HIV-1 p24 ELISA, and GFP-based viral infection assays, we show that the combination knockout of CCR5, MOGS, and viral sequences profoundly reduces HIV-1 replication in an ex vivo cellular model, that is, HIV-1-infected peripheral blood mononuclear human cells, thus offering a pathway to launch further preclinical studies.
Z. Safaei, Anna Bellizzi, Hong Liu et al.· Human Gene Therapy· 0 citations
HIV-SCRIBE is developed, a CRISPR-based molecular recorder in which a self-targeting guide RNA locus is placed under a Tat-responsive minimal HIV-1 5'LTR promoter, coupling Cas9-mediated cleavage and error-prone repair to Tat-driven transcriptional activation to generate a durable molecular record of HIV-1 reactivation and, more broadly, of cell-type-specific CRISPR editing dynamics.
Nahia Urturi Ortiz, M. Nonnemacher, Brian Wigdahl· 0 citations
Cancer immunotherapy targeting B-cell specific CD19 antigen meant a major breakthrough in the treatment of B-cell malignancies. Yet, vast proportion of treated patients experience relapse and failure of the therapy. Although multiple mechanisms of CD19-immunotherapy failure have been described, CD19-negative relapses represent the major hurdle in achieving higher and durable response rates. Our established in vitro co-culture models revealed that suboptimal CAR-T cell performance, inefficient to mediate target cell killing, results in robust downregulation of CD19 target antigen. Using genome-wide CRISPR screening, we addressed the mechanisms responsible for such CD19 downregulation and identified Cullin-1 and CD81 playing instrumental role in negative and positive regulation of CD19 expression, respectively. Inhibiting Cullin-1 activity with pevonedistat prevents the loss of CD19 under immunotherapeutic pressure, results in higher CD19 surface levels and consequently enhances the efficacy of target cell killing by CD19-CAR-T cells, CD19-CAR-NK cells and CD19-targeting antibody treatment. Mechanistically, we show that pevonedistat blocks the degradation of CD19 upon its internalization and allows its recycling back to the plasma membrane. CD81 chaperone protein is critically involved in this process as the absence of CD81 abrogates the effect of pevonedistat. In summary, we identify Cullin-1 as a novel and druggable regulator of CD19 protein stability. Cullin-1 inhibition augments CD19 surface expression, thereby improving the efficiency of CD19-targeting immunotherapies, thus arguing for potential incorporation of pevonedistat into novel combination therapies. Key Points Cullin-1 inhibition stabilizes CD19 surface expression, preventing its loss under immunotherapeutic pressure Pevonedistat treatment enhances the efficacy of CD19-CAR-T cells, CAR-NK cells and CD19-targeting antibodies
N. V. Gottumukkala, Tomáš Loja, M. Šmída· bioRxiv· 0 citations
HIV-1 Vpr is abundantly packaged into virions and remodels host cells immediately after entry. Here, using high-efficiency HIV-1 infection protocols and unbiased proteomics in primary CD4+ T cells, we identify the T cell fate regulator TCF7 (TCF-1) as a previously unrecognized Vpr target. Virion-delivered Vpr rapidly depleted TCF7 in both resting and activated CD4+ T cells, which was a conserved activity of diverse Vpr proteins. The activity was independent of canonical Vpr substrate engagement but resulted terminally in proteasomal degradation of TCF7. TCF7 suppressed HIV-1 production and Env incorporation, whereas its depletion promoted loss of stem-like properties and differentiation toward effector phenotypes. Accordingly, effector T cell differentiation states are associated with productive HIV-1 infection and reduced TCF7 abundance. Thus, Vpr-mediated TCF7 depletion couples enhanced viral fitness to reprogramming of CD4+ T cell identity, generating permissive differentiated cells while impairing the maintenance of effective antiviral immunity via reduced T cell stemness.
Johanna Leyens, Anthea Darius, Carlos Alberto Vanegas-Torres et al.· bioRxiv· 0 citations
Bispecific antibodies that reroute cytotoxic effectors toward infected cells are promising HIV-1 cure agents, yet existing formats bind Env and are limited by antigenic variation and Env down-regulation. We engineered a TCR-mimic single-chain diabody, HI12, that recognizes a conserved Pol-derived peptide presented by HLA-A*02:01 and evaluated its effect in HLA-matched, HIV-infected humanized mice. When administered during early antiretroviral therapy (ART), HI12 was well tolerated, activated CD8+ T cells, and accelerated plasma virus decay. Treatment produced three- to eightfold reductions in intact and total proviral DNA within lymph-node and splenic CD4+ T cells, indicating substantive reservoir clearance. After ART interruption, HI12-treated animals showed a significant delay in viral rebound compared with controls, linking reservoir reduction to improved posttherapy control. These findings provide in vivo evidence that a peptide-HLA-directed bispecific antibody can both shrink the intact HIV reservoir and defer viral recrudescence, supporting further development of TCR-mimic bispecific antibodies for cure strategies.
Zhe Yuan, N. Board, Miaoyun Zhao et al.· Proceedings of the National...· 0 citations